A patient with a 6-yr history of chronic orofacial pain and periapical pathosis in the anterior maxilla presented for evaluation and treatment. Previous root canal therapy had failed to resolve the persistent pain. Further evaluation suggested a non-odontogenic etiology of the patient's symptoms. Exploratory surgery revealed an osseous cavity across the maxillary anterior palatal midline filled with osteoid and early mineralized bone. The tumor was surgically removed in toto. A diagnosis of benign osteoblastoma was made.