Rare TCF3 variants associated with pediatric B cell acute lymphoblastic leukemia

Pediatr Hematol Oncol. 2024;41(1):81-87. doi: 10.1080/08880018.2023.2201302. Epub 2023 May 2.

Abstract

Germline genetic variants influence development of pediatric B cell acute lymphoblastic leukemia (B-ALL). Genome-wide association studies (GWAS) have identified several pediatric B-ALL susceptibility loci. IKZF1 and PAX5, transcription factors involved in B cell development, have been reported as susceptibility genes for B-ALL development. Therefore, we hypothesized that rare variants of genes involved in B cell development would be candidate susceptibility loci for pediatric B-ALL. Thus, we sequenced TCF3, a key transcription factor gene involving in B cell development. Saliva DNA from 527 pediatric patients with pediatric B-ALL in remission who were registered with the Tokyo Children's Cancer Study Group (TCCSG) were examined. As a TCF3 gene-based evaluation, the numbers of rare deleterious germline TCF3 sequence variants in patients with pediatric B-ALL were compared with those in cancer-free individuals using data in public databases. As a TCF3 single-variant evaluation, the frequencies of rare deleterious germline TCF3 sequence variants in patients with pediatric B-ALL were also compared with those in control data. TCF3 gene-based analysis revealed significant associations between rare deleterious variants and pediatric B-ALL development. In addition, TCF3 variant-based analysis showed particularly strong association between variant rs372168347 (three in 521 TCCSG and three in the 15780 gnomAD whole genome analysis cohort, p = 0.0006) and pediatric B-ALL development. TCF3 variants are known to influence B cell maturation and may increase the risk of preleukemic clone emergence.

Keywords: Acute lymphoblastic leukemia; TCF3; child; variant.

MeSH terms

  • Basic Helix-Loop-Helix Transcription Factors / genetics
  • Burkitt Lymphoma*
  • Child
  • Genome-Wide Association Study
  • Humans
  • Oncogene Proteins, Fusion / genetics
  • Precursor B-Cell Lymphoblastic Leukemia-Lymphoma* / genetics
  • Transcription Factors / genetics

Substances

  • Oncogene Proteins, Fusion
  • Transcription Factors
  • TCF3 protein, human
  • Basic Helix-Loop-Helix Transcription Factors