Case Report: An extremely rare case of double extralobar pulmonary sequestration with anomalous supplying arteries originating from the abdominal aorta in the left thoracic cavity

Longfei Lv; Yunpeng Zhai; Huashan Zhao; Rui Guo; Hongxiu Xu; Shisong Zhang

doi:10.3389/fped.2022.926942

Case Report: An extremely rare case of double extralobar pulmonary sequestration with anomalous supplying arteries originating from the abdominal aorta in the left thoracic cavity

Front Pediatr. 2022 Jul 22:10:926942. doi: 10.3389/fped.2022.926942. eCollection 2022.

Authors

Longfei Lv^{1

2}, Yunpeng Zhai^{1

2}, Huashan Zhao^{1

2}, Rui Guo^{1

2}, Hongxiu Xu^{1

2}, Shisong Zhang^{1

2}

Affiliations

¹ Department of Thoracic and Oncological Surgery, Children's Hospital Affiliated to Shandong University, Jinan, China.
² Department of Thoracic and Oncological Surgery, Jinan Children's Hospital, Jinan, China.

Abstract

To the best of our knowledge, double or multiple extralobar pulmonary sequestrations (PSs) with anomalous arterial supply in the ipsilateral thoracic cavity have rarely been reported before. PS can be divided into two types: intralobar sequestration (ILS) and extralobar sequestration (ELS). We encountered a 5-month-old infant with double ELS in the left thoracic cavity that was incidentally detected during thoracoscopic surgery. Surgical exploration revealed two separate, well-circumscribed abnormal masses in the left thoracic cavity, and the patient was successfully treated using thoracoscopic surgery. Postoperative pathology confirmed that both masses were PS tissues. Accurate preoperative diagnosis using CT alone may be inadequate in this type of case. Therefore, thoracoscopy may be more suitable for diagnosing and treating unusual ELS.

Keywords: congenital lung malformation; extralobar sequestration; intralobar sequestration; pulmonary sequestration; thoracoscopic surgery.

Publication types

Case Reports