SLC20A2-related primary familial brain calcification with purely acute psychiatric symptoms: a case report

BMC Neurol. 2022 Jul 18;22(1):265. doi: 10.1186/s12883-022-02798-9.

Abstract

Background: Primary familial brain calcification (PFBC) is a rare inherited neurological disorder characterized by bilateral basal ganglia calcification with a series of motor and nonmotor symptoms. Mutations in the SLC20A2 gene, encoding the PiT2 protein, are the major cause of the disease. Here, we report a Chinese PFBC family carrying a SLC20A2 gene mutation, and the proband presented with purely acute psychiatric symptoms, which has been rarely reported in this disease.

Case presentation: A 38-year-old woman was hospitalized due to disorganized speech; disordered thought contents; disorganized behaviour; emotional instability and lability; and grandiose words, actions and facial expressions. Brain computerized tomography (CT) revealed calcification in the basal ganglia; cerebellar dentate nuclei; and subcortical, periventricular, and deep white matter regions in she and her family members. Through mutation analysis, a heterozygous truncating mutation, c.1723G > T, p.(Glu575*), was identified in the SLC20A2 gene in this family. Thus, this patient was diagnosed with genetically confirmed PFBC, and she responded well to a low dose of antipsychotic drugs. The penetrance of the disease in this family was only 33%, which was significantly lower than that in most families carrying SLC20A2 gene mutations.

Conclusions: Patients with SLC20A2-related PFBC might present with psychiatric symptoms alone, and the penetrance of the disease may be quite low, which adds to the clinical heterogeneity of the disease.

Keywords: Case report; Mutation; Primary familial brain calcification; Psychiatric symptoms; SLC20A2 gene.

Publication types

  • Case Reports

MeSH terms

  • Adult
  • Basal Ganglia / metabolism
  • Basal Ganglia Diseases* / complications
  • Basal Ganglia Diseases* / diagnostic imaging
  • Basal Ganglia Diseases* / genetics
  • Brain
  • Brain Diseases* / complications
  • Brain Diseases* / diagnostic imaging
  • Brain Diseases* / genetics
  • Calcinosis* / complications
  • Calcinosis* / diagnostic imaging
  • Calcinosis* / genetics
  • Female
  • Humans
  • Mutation / genetics
  • Sodium-Phosphate Cotransporter Proteins, Type III / genetics

Substances

  • SLC20A2 protein, human
  • Sodium-Phosphate Cotransporter Proteins, Type III