TMEM151A phenotypic spectrum includes paroxysmal kinesigenic dyskinesia with infantile convulsions

Neurol Sci. 2022 Oct;43(10):6095-6099. doi: 10.1007/s10072-022-06208-3. Epub 2022 Jun 21.

Abstract

In a three-generation family, five individuals exhibited the typical phenotype of paroxysmal kinesigenic dyskinesia (PKD). Intriguingly, one of the individuals also showed benign familial infantile convulsions (BFIC) at age 4 months and spontaneously resolved at age 18 months. At age 12, she developed a typical PKD, and was gradually relieved at age 21. Therefore, the clinical phenotype was consistent with PKD with infantile convulsions (PKD/IC). Whole exome sequence and co-segregation analysis revealed a novel heterozygous variant c.1085A > G in the TMEM151A gene. Our study suggests that the TMEM151A gene may be associated with the disease spectrum of PKD-PKD/IC-BFIC.

Keywords: PRRT2 gene; Paroxysmal kinesigenic dyskinesia; Paroxysmal kinesigenic dyskinesia with infantile convulsions,; TMEM151A gene.

MeSH terms

  • Dystonia
  • Epilepsy, Benign Neonatal* / diagnosis
  • Epilepsy, Benign Neonatal* / genetics
  • Female
  • Humans
  • Membrane Proteins / genetics
  • Mutation / genetics
  • Nerve Tissue Proteins* / genetics
  • Pedigree
  • Phenotype
  • Seizures / genetics

Substances

  • Membrane Proteins
  • Nerve Tissue Proteins

Supplementary concepts

  • Familial paroxysmal dystonia