[A case of myopathy, myocarditis, and encephalitis with nonconvulsive status epileptics after immune checkpoint inhibitor therapy for ureter cancer]

Rinsho Shinkeigaku. 2022 May 31;62(5):395-398. doi: 10.5692/clinicalneurol.cn-001725. Epub 2022 Apr 26.
[Article in Japanese]

Abstract

A 72-year-old man, who had received pembrolizumab of immune checkpoint inhibitor (ICI) over 6 months for ureter cancer, developed progressive skeletal muscle weakness, dysarthria, dyspnea, and consciousness disturbance over the past two weeks. The systemic work-up tests documented an encephalitis, myopathy, and myocarditis. Multiple autoimmune antibodies of anti-Tr, anti-titin, anti-kv1.4, anti-GM1 and anti-GD1a were positive in the serum. Although myopathy and myocarditis responded to high-dose steroid pulse therapy, encephalopathy deteriorated. Electroencephalogram showed a fluctuated pattern of rhythmic delta activity with fast waves, and a rapid response to intravenous diazepam revealed a condition of nonconvulsive status epileptics (NCSE). The patient had an uneventful course after anti-epileptic medication. The ICIs therapy may trigger a broader activation of multiple autoimmune mechanisms. When an encephalitis by immune-related adverse events does not respond to standard immunotherapy, NCSE may be a main pathophysiological mechanism, thereby anti-epileptics being an alternative treatment option.

Keywords: encephalitis; immune checkpoint inhibitor (ICI); immune-related adverse events (irAE); myopathy; nonconvulsive status epileptics (NCSE).

Publication types

  • Case Reports

MeSH terms

  • Aged
  • Anticonvulsants / therapeutic use
  • Encephalitis* / chemically induced
  • Encephalitis* / diagnosis
  • Encephalitis* / drug therapy
  • Humans
  • Immune Checkpoint Inhibitors
  • Male
  • Muscular Diseases* / drug therapy
  • Myocarditis* / chemically induced
  • Myocarditis* / drug therapy
  • Ureteral Neoplasms* / drug therapy

Substances

  • Anticonvulsants
  • Immune Checkpoint Inhibitors