Case Report: A Novel TNFAIP3 Mutation Causing Haploinsufficiency of A20 With a Lupus-Like Phenotype

Front Immunol. 2021 Feb 19:12:629457. doi: 10.3389/fimmu.2021.629457. eCollection 2021.

Abstract

Genetic mutations that result in loss-of-function of the protein A20 result in an early-onset autoinflammatory disease-haploinsufficiency of A20 (HA20). The reported clinical presentations of HA20 include a Behcet's disease-like phenotype and a more lupus-like phenotype. We have identified a novel mutation in the gene encoding A20 in a pediatric patient with chronic lymphadenopathy, lupus-like symptoms, and progressive hypogammaglobulinemia. This case illustrates the wide range of clinical symptoms, including immunodeficiency, that can occur in patients with HA20.

Keywords: A20; case report; haploinsufficiency of A20; hypogammaglobulinemia; lupus; lymphadenopathy; tumor necrosis factor alpha-induced protein 3.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Agammaglobulinemia / diagnosis
  • Agammaglobulinemia / drug therapy
  • Agammaglobulinemia / genetics*
  • Agammaglobulinemia / immunology
  • DNA Mutational Analysis
  • Diagnosis, Differential
  • Female
  • Genetic Predisposition to Disease
  • Glucocorticoids / therapeutic use
  • Haploinsufficiency*
  • Hereditary Autoinflammatory Diseases / diagnosis
  • Hereditary Autoinflammatory Diseases / drug therapy
  • Hereditary Autoinflammatory Diseases / genetics*
  • Hereditary Autoinflammatory Diseases / immunology
  • Heredity
  • Humans
  • Immunosuppressive Agents / therapeutic use
  • Loss of Function Mutation*
  • Lupus Erythematosus, Systemic / diagnosis
  • Lupus Erythematosus, Systemic / genetics*
  • Lupus Erythematosus, Systemic / immunology
  • Lymphadenopathy / diagnosis
  • Lymphadenopathy / drug therapy
  • Lymphadenopathy / genetics*
  • Lymphadenopathy / immunology
  • Pedigree
  • Phenotype
  • Predictive Value of Tests
  • Treatment Outcome
  • Tumor Necrosis Factor alpha-Induced Protein 3 / genetics*

Substances

  • Glucocorticoids
  • Immunosuppressive Agents
  • TNFAIP3 protein, human
  • Tumor Necrosis Factor alpha-Induced Protein 3