Systemic sclerosis skin is a primed microenvironment for soft tissue calcification-a hypothesis

Rheumatology (Oxford). 2021 Jun 18;60(6):2517-2527. doi: 10.1093/rheumatology/keab156.

Abstract

Calcinosis cutis, defined as sub-epidermal deposition of calcium salts, is a major clinical problem in patients with SSc, affecting 20-40% of patients. A number of recognized factors associated with calcinosis have been identified, including disease duration, digital ischaemia and acro-osteolysis. Yet, to date, the pathogenesis of SSc-related calcinosis remains unknown, and currently there is no effective disease-modifying pharmacotherapy. Following onset of SSc, there are marked changes in the extracellular matrix (ECM) of the skin, notably a breakdown in the microfibrillar network and accumulation of type I collagen. Our hypothesis is that these pathological changes reflect a changing cellular phenotype and result in a primed microenvironment for soft tissue calcification, with SSc fibroblasts adopting a pro-osteogenic profile, and specific driving forces promoting tissue mineralization. Considering the role of the ECM in disease progression may help elucidate the mechanism(s) behind SSc-related calcinosis and inform the development of future therapeutic interventions.

Keywords: calcinosis; dermal fibroblasts; elastin-derived peptides; osteogenic differentiation; systemic sclerosis.

Publication types

  • Review

MeSH terms

  • Calcinosis / etiology*
  • Cell Differentiation
  • Cell Hypoxia / physiology
  • Cellular Microenvironment*
  • Collagen Type I / metabolism
  • Disease Progression
  • Elastin / metabolism
  • Extracellular Matrix / metabolism
  • Fibrillin-1 / genetics
  • Fibroblasts / cytology
  • Fibroblasts / physiology*
  • Glucose Transporter Type 1 / metabolism
  • Humans
  • Mesenchymal Stem Cells / cytology
  • Mesenchymal Stem Cells / physiology
  • Myofibroblasts / cytology
  • Osteoblasts / cytology
  • Osteogenesis
  • Osteolysis / metabolism
  • Phenotype
  • Phosphates / metabolism
  • Scleroderma, Systemic / complications*
  • Scleroderma, Systemic / metabolism
  • Scleroderma, Systemic / pathology
  • Skin / cytology
  • Transforming Growth Factor beta / metabolism
  • Vascular Endothelial Growth Factor A / metabolism

Substances

  • Collagen Type I
  • FBN1 protein, human
  • Fibrillin-1
  • Glucose Transporter Type 1
  • Phosphates
  • Transforming Growth Factor beta
  • Vascular Endothelial Growth Factor A
  • Elastin