A Unique Genomic Variant of HDR Syndrome in Newborn

Indian Pediatr. 2018 Aug 15;55(8):705-706.

Abstract

Background: HDR syndrome (also known as Barakat syndrome) is a rare genetic disorder due to deletions/mutations on specific regions of zinc-finger transcription factor (GATA3) gene.

Case characteristics: A male preterm infant presented with multiple dysmorphic features characterized by small for gestational age, hypognathia and facial abnormalities.

Observation: Investigations revealed hypocalcemia and low parathyroid hormone levels and bilateral sensorineural deafness.

Outcome: Chromosomal microarray analysis revealed a combination of deletion on chromosome 10p (10p15.3p14) with loss of GATA3 gene and duplication of chromosome 20p (20p13p12.3) as a result of unbalanced 10:20 translocation.

Message: Detecting this syndrome at neonatal age is very important because it allows early intervention to minimize future clinical problems.

Publication types

  • Case Reports

MeSH terms

  • Base Sequence*
  • Chromosomes, Human, Pair 10*
  • Chromosomes, Human, Pair 20
  • GATA3 Transcription Factor / genetics*
  • Genetic Markers
  • Hearing Loss, Sensorineural / diagnosis*
  • Hearing Loss, Sensorineural / genetics
  • Humans
  • Hypoparathyroidism / diagnosis*
  • Hypoparathyroidism / genetics
  • Infant, Newborn
  • Infant, Premature
  • Infant, Premature, Diseases / diagnosis*
  • Infant, Premature, Diseases / genetics
  • Male
  • Nephrosis / diagnosis*
  • Nephrosis / genetics
  • Sequence Deletion*
  • Trisomy / diagnosis*

Substances

  • GATA3 Transcription Factor
  • GATA3 protein, human
  • Genetic Markers

Supplementary concepts

  • Barakat syndrome
  • Trisomy 20p