Founder Mutations for Early Onset Melanoma as Revealed by Whole Exome Sequencing Suggests That This is Not Associated with the Increasing Incidence of Melanoma in Poland

Cancer Res Treat. 2019 Jan;51(1):337-344. doi: 10.4143/crt.2018.157. Epub 2018 May 14.

Abstract

Purpose: Germline mutations within melanoma susceptibility genes are present only in minority of melanoma patients and it is expected that additional genes will be discovered with next generation sequence technology and whole-exome sequencing (WES).

Materials and methods: Herein we performed WES on a cohort of 96 unrelated Polish patients with melanoma diagnosed under the age of 40 years who all screened negative for the presence of CDKN2Avariants. A replication study using a set of 1,200 melanoma patient DNA samples and similarly large series of healthy controls was undertaken.

Results: We selected 21 potentially deleterious variants in 20 genes (VRK1, MYCT1, DNAH14, CASC3, MS4A12, PRC1, WWOX, CARD6, EXO5, CASC3, CASP8AP2, STK33, SAMD11, CNDP2, CPNE1, EFCAB6, CABLES1, LEKR1, NUDT17, and RRP15), which were identified by WES and confirmed by Sanger sequencing for an association study. Evaluation of the allele distribution among carriers and their relatives in available family trios revealed that these variants were unlikely to account for many familial cases of melanoma. Replication study revealed no statistically significant differences between cases and controls.

Conclusion: Although most of the changes seemed to be neutral we could not exclude an association between variants in VRK1, CREB3L3, EXO5, and STK33 with melanoma risk.

Keywords: Frameshift mutation; Melanoma; Whole exome sequencing.

MeSH terms

  • Adolescent
  • Adult
  • Cyclic AMP Response Element-Binding Protein / genetics
  • Exome Sequencing / methods*
  • Exonucleases / genetics
  • Female
  • Genetic Predisposition to Disease / genetics*
  • Germ-Line Mutation*
  • Humans
  • Intracellular Signaling Peptides and Proteins / genetics
  • Male
  • Melanoma / genetics*
  • Pedigree
  • Poland
  • Protein Serine-Threonine Kinases / genetics
  • Young Adult

Substances

  • CREB3L3 protein, human
  • Cyclic AMP Response Element-Binding Protein
  • Intracellular Signaling Peptides and Proteins
  • Protein Serine-Threonine Kinases
  • STK33 protein, human
  • VRK1 protein, human
  • EXO5 protein, human
  • Exonucleases