A novel heterozygous mutation in the Birt-Hogg-Dubé Syndrome

Arch Esp Urol. 2017 Sep;70(7):675-678.

Abstract

Objetive: Our aim is to present a novel mutation of the Birt-Hogg-Dubé Syndrome.

Methods: We present a case report of a 70-year-old male with three solid nodulary lesions of 4, 2.6, and 3 cm each in the right kidney, and two lesions of 1.5 and 1.3 cm in the left kidney.

Results: Needle biopsy was performed. The pathological analysis of right kidney lesions revealed a renal tumor suggestive of chromophobe renal cell carcinoma and medullar tumor with zones that suggested oncocytosis. Genetic test results were positive for a novel heterozygous mutation c.1198G>A; p.V400I in exon 11 of the FLCN gene.

Conclusion: In patients presenting with bilateral multifocal renal tumors of oncocytic hybrid histology, Birt- Hogg-Dubé syndrome should be the first diagnosis in mind. The mutation found in this patient has not been previously described in the literature in the context of BHD.

Publication types

  • Case Reports

MeSH terms

  • Aged
  • Birt-Hogg-Dube Syndrome / genetics*
  • Carcinoma, Renal Cell / genetics*
  • Heterozygote
  • Humans
  • Kidney Neoplasms / genetics*
  • Male
  • Mutation*