Chewing-induced facial dystonia: a rare presentation of task-specific dystonia

BMJ Case Rep. 2017 Jul 17:2017:bcr2016218956. doi: 10.1136/bcr-2016-218956.

Abstract

This case is an addition to scarce literature available for a rare condition, chewing-induced task-specific dystonia. The patient was a 63-year-old woman who presented with a 4-year history of progressive difficulty in eating food only during chewing associated with abnormal facial grimaces without any difficulty in drinking, swallowing, speaking or singing. Examination revealed dystonia of facial muscles every time she chewed but absent during drinking and speaking. As movements were consistent and reproducible with the specific task, other differential diagnosis like motor tics, psychogenic disorder, tardive dystonia and parkinsonism syndrome were excluded leading to a diagnosis of task-specific facial dystonia triggered by chewing. Treatment was started with trihexyphenidyl and later on tetrabenazine was also added but she got only mild relief of symptoms. As she did not agreed for botulinum toxin therapy, so we continued with the same treatment without much improvement.

Keywords: Medical Management; Movement Disorders (other Than Parkinsons); Neurology (drugs And Medicines).

Publication types

  • Case Reports

MeSH terms

  • Dystonia* / therapy
  • Dystonic Disorders* / drug therapy
  • Face*
  • Facial Muscles / pathology*
  • Female
  • Humans
  • Mastication*
  • Middle Aged
  • Tetrabenazine / therapeutic use
  • Trihexyphenidyl / therapeutic use

Substances

  • Trihexyphenidyl
  • Tetrabenazine

Supplementary concepts

  • Dystonia, Focal, Task-Specific