Accurately annotate compound effects of genetic variants using a context-sensitive framework

Nucleic Acids Res. 2017 Jun 2;45(10):e82. doi: 10.1093/nar/gkx041.

Abstract

In genomics, effectively identifying the biological effects of genetic variants is crucial. Current methods handle each variant independently, assuming that each variant acts in a context-free manner. However, variants within the same gene may interfere with each other, producing combinational (compound) rather than individual effects. In this work, we introduce COPE, a gene-centric variant annotation tool that integrates the entire sequential context in evaluating the functional effects of intra-genic variants. Applying COPE to the 1000 Genomes dataset, we identified numerous cases of multiple-variant compound effects that frequently led to false-positive and false-negative loss-of-function calls by conventional variant-centric tools. Specifically, 64 disease-causing mutations were identified to be rescued in a specific genomic context, thus potentially contributing to the buffering effects for highly penetrant deleterious mutations. COPE is freely available for academic use at http://cope.cbi.pku.edu.cn.

MeSH terms

  • Epistasis, Genetic*
  • Genetic Variation
  • Genome, Human
  • Genomics / methods*
  • High-Throughput Nucleotide Sequencing
  • Humans
  • Molecular Sequence Annotation / methods*
  • Mutation
  • Software*