[Congenital erythropoietic porphyria : An update]

Hautarzt. 2016 Mar;67(3):216-20. doi: 10.1007/s00105-015-3732-8.
[Article in German]

Abstract

Background: Congenital erythropoetic porphria is a very rare type of autosomal recessive nonacute porphyria. Homozygous or compound heterozygous mutations in the uroporphyrinogen III consynthase gene cause a marked enzymatic deficiency of uroporphyrinogen III consynthase, the fourth enzyme along the heme biosynthetic pathway.

Clinical presentation: Clinically, affected patients are characterized by a moderate to severe photosensitivity. Starting early in infancy, they develop blisters, erosions, and exulcerations in sun-exposed areas of the body, often resulting in scar formation and mutilation. Besides the cutaneous changes, hemolytic anemia, transfusion-dependent pancytopenia, hepatosplenomegaly and liver cirrhosis can occur. Due to increased susceptibility for infections and because of the hematological and hepatic complications, affected individuals have a decreased life expectancy, rarely exceeding 40 years of age.

Treatment: Currently, no causal treatment is available for the disorder. Therefore, the most important therapeutic modality is strict avoidance of sunlight, preferably by inversion of the day-night rhythm, or at least consequent photoprotection with adequate clothing. In severe cases, bone marrow or stem cell transplantation should be considered.

Keywords: Gunther disease; Heme biosynthesis; Porphyrias; Sunscreening agents; Uroporphyrinogen III synthetase.

Publication types

  • Review

MeSH terms

  • Evidence-Based Medicine
  • Humans
  • Porphyria, Erythropoietic / diagnosis*
  • Porphyria, Erythropoietic / epidemiology
  • Porphyria, Erythropoietic / therapy*
  • Prevalence
  • Radiation Protection / methods*
  • Risk Factors
  • Sunlight
  • Sunscreening Agents / therapeutic use*
  • Treatment Outcome

Substances

  • Sunscreening Agents