Cystic Fibrosis from Laboratory to Bedside: The Role of A20 in NF-κB-Mediated Inflammation

Med Princ Pract. 2015;24(4):301-10. doi: 10.1159/000381423. Epub 2015 Apr 25.

Abstract

Cystic fibrosis (CF) is a lifelong, inflammatory multi-organ disease and the most common lethal, genetic condition in Caucasian populations, with a median survival rate of 41.5 years. Pulmonary disease, characterized by infective exacerbations, bronchiectasis and increasing airway insufficiency is the most serious manifestation of this disease process, currently responsible for over 80% of CF deaths. Chronic dysregulation of the innate immune and host inflammatory response has been proposed as a mechanism central to this genetic condition, primarily driven by the nuclear factor κB (NF-κB) pathway. Chronic activation of this transcription factor complex leads to the production of pro-inflammatory cytokines and mediators such as IL-6, IL-8 and TNF-α. A20 has been described as a central and inducible negative regulator of NF-κB. This intracellular molecule negatively regulates NF-κB-driven pro-inflammatory signalling upon toll-like receptor activation at the level of TRAF6 activation. Silencing of A20 increases cellular levels of p65 and induces a pro-inflammatory state. We have previously shown that A20 expression positively correlates with lung function (FEV1%) in CF. Despite improvement in survival rates in recent years, advancements in available therapies have been incremental. We demonstrate that the experimental use of naturally occurring plant diterpenes such as gibberellin on lipopolysaccharide-stimulated cell lines reduces IL-8 release in an A20-dependent manner. We discuss how the use of a novel bio-informatics gene expression connectivity-mapping technique to identify small molecule compounds that similarly mimic the action of A20 may lead to the development of new therapeutic approaches capable of reducing chronic airway inflammation in CF.

Publication types

  • Review

MeSH terms

  • Cell Culture Techniques
  • Chromosome Mapping
  • Cystic Fibrosis / physiopathology*
  • Cytokines / biosynthesis*
  • DNA-Binding Proteins / metabolism
  • Humans
  • Inflammation / metabolism*
  • Inflammation Mediators / metabolism*
  • Interleukin-6 / biosynthesis
  • Interleukin-8 / biosynthesis
  • Intracellular Signaling Peptides and Proteins / metabolism
  • NF-kappa B / metabolism*
  • Neoplasm Proteins / metabolism
  • Nuclear Proteins / metabolism
  • Phenotype
  • Signal Transduction
  • Toll-Like Receptors / metabolism
  • Tumor Necrosis Factor alpha-Induced Protein 3
  • Tumor Necrosis Factor-alpha / biosynthesis

Substances

  • Cytokines
  • DNA-Binding Proteins
  • Inflammation Mediators
  • Interleukin-6
  • Interleukin-8
  • Intracellular Signaling Peptides and Proteins
  • NF-kappa B
  • Neoplasm Proteins
  • Nuclear Proteins
  • TAX1BP1 protein, human
  • TNF protein, human
  • Toll-Like Receptors
  • Tumor Necrosis Factor-alpha
  • TNFAIP3 protein, human
  • Tumor Necrosis Factor alpha-Induced Protein 3