A retrospective study of childhood urolithiasis was performed from July 1978 to December 1989 in the National Taiwan University Hospital. During the eleven years, fourteen patients aged from 1 to 16 years were enrolled. The male to female ratio was 10:4, but no sex predilection was found in seven children with bladder stone(s) (M:F = 4:3), Hematuria and pyuria were the commonest symptoms and signs. Bladder stone was the most frequently encountered stone while renal stone was the second. The underlying factors included urinary tract anomalies, and surgical intervention of the urinary tract and trauma. Proteus species was the most common bacterium isolated from the urine of stone patients. However, half of the patients' urine specimens were sterile. Calcium oxalate and struvite were the two main components of the stones irrespective of renal, ureteral, or bladder stone origin. Lithotomy, endourological removal, and extracorporeal shock wave lithotripsy were the major therapeutic procedures, but the last procedure might replace the others.