Ex vivo transduction and transplantation of bone marrow cells for liver gene delivery of alpha1-antitrypsin

Mol Ther. 2010 Aug;18(8):1553-8. doi: 10.1038/mt.2010.116. Epub 2010 Jun 15.

Abstract

Adult stem cell-based gene therapy holds several unique advantages including avoidance of germline or other undesirable cell transductions. We have previously shown that liver progenitor (oval) cells can be used as a platform for liver gene delivery of human alpha1-antitrypsin (hAAT). However, this cell source cannot be used in humans for autologous transplantation. In the present study, we tested the feasibility of bone marrow (BM) cell-based liver gene delivery of hAAT. In vitro studies showed that BM cells can be transduced by lentiviral vector (Lenti-CB-hAAT) and recombinant adeno-associated viral vectors (rAAV1-CB-hAAT, and rAAV8-CB-hAAT). Transplantation studies showed that transplanted BM cells homed into liver, differentiated into hepatocytes and expressed hAAT in the liver. Importantly, we showed that transplantation of rAAV8-CB-hAAT vector-transduced BM cells resulted in sustained levels of hAAT in the systemic circulation of recipient mice. These results demonstrated that rAAV vector-mediated BM cell-based liver gene therapy is feasible for the treatment of AAT deficiency and implies a novel therapy for the treatment of liver diseases.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adenoviridae / genetics
  • Albumins / genetics
  • Albumins / metabolism
  • Animals
  • Cells, Cultured
  • Enzyme-Linked Immunosorbent Assay
  • Female
  • Genetic Vectors / genetics
  • Green Fluorescent Proteins / genetics
  • Green Fluorescent Proteins / metabolism
  • Humans
  • In Situ Hybridization
  • Liver / metabolism*
  • Male
  • Mice
  • Mice, Inbred C57BL
  • Transduction, Genetic / methods
  • Y Chromosome / metabolism
  • alpha 1-Antitrypsin / blood
  • alpha 1-Antitrypsin / genetics
  • alpha 1-Antitrypsin / metabolism*

Substances

  • Albumins
  • alpha 1-Antitrypsin
  • Green Fluorescent Proteins