Ameloblastomas are benign odontogenic tumors but are locally aggressive, most commonly occurring in the mandible and in the third to fifth decade of life. The male-to-female ratio is approximately equal. Recurrence of ameloblastoma due to inadequate treatment is often described. Recurrences in the temporal area are very rare and are related to the type of primary treatment. The authors describe a case of ameloblastoma recurrence in the temporal area and review the literature regarding recurrence and treatment.