Only few cases of extraparotid localizations of pleomorphic adenoma (PA) were reported in literature: at the lips, tonsils of the tongue, the occipital area and of the nasal septum, retropharyngeal area, temporal bone, and the thyroglossal and pituitary ducts.The finding of a PA in the minor salivary glands of the cheek was described only in 2 cases during the last 24 years and represented an exceptional finding.The aim of this article was to illustrate a case of extraparotid PA developing at the salivary glands of cheek, a short distance from Stensen duct, and to report surgical strategy.