Myelomastocytic leukemia: evidence for the origin of mast cells from the leukemic clone and eradication by allogeneic stem cell transplantation

Clin Cancer Res. 2005 Oct 1;11(19 Pt 1):6787-92. doi: 10.1158/1078-0432.CCR-05-1064.

Abstract

Purpose: Myelomastocytic leukemia is a term used for patients with advanced myeloid neoplasms, in whom elevated numbers of immature atypical mast cells are found, but criteria for a primary mast cell disease are not met. The origin of mast cells in these patients is presently unknown.

Patient and methods: We have analyzed clonality of mast cells in an 18-year-old patient suffering from acute myeloid leukemia with a complex karyotype including a t(8;21) and mastocytic transformation with a huge increase in immature mast cells and elevated serum tryptase level, but no evidence for a primary mast cell disease/mastocytosis.

Results: As assessed by in situ fluorescence hybridization combined with tryptase staining, both the tryptase-negative blast cells and the tryptase-positive mast cells were found to contain the t(8;21)-specific AML1/ETO fusion gene. Myeloablative stem cell transplantation resulted in complete remission with consecutive disappearance of AML1/ETO transcripts, decrease of serum tryptase to normal range, and disappearance of neoplastic mast cells.

Conclusion: These data suggest that mast cells directly derive from the leukemic clone in patients with myelomastocytic leukemia.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Antigens, CD34 / biosynthesis
  • Biomarkers, Tumor
  • Bone Marrow Cells / metabolism
  • CD2 Antigens / biosynthesis
  • Chromosomes, Human, Pair 21 / genetics
  • Chromosomes, Human, Pair 8 / genetics
  • Flow Cytometry
  • Granulocyte Precursor Cells / metabolism
  • Humans
  • Immunophenotyping
  • In Situ Hybridization, Fluorescence
  • Karyotyping
  • Leukemia, Myeloid, Acute / diagnosis*
  • Leukemia, Myeloid, Acute / genetics*
  • Leukemia, Myeloid, Acute / pathology
  • Male
  • Mast Cells / cytology*
  • Mast Cells / metabolism
  • Proto-Oncogene Proteins c-kit / biosynthesis
  • Receptors, Interleukin-2 / biosynthesis
  • Serine Endopeptidases / blood
  • Serine Endopeptidases / metabolism
  • Stem Cell Transplantation / methods*
  • Translocation, Genetic
  • Transplantation, Homologous
  • Tryptases

Substances

  • Antigens, CD34
  • Biomarkers, Tumor
  • CD2 Antigens
  • Receptors, Interleukin-2
  • Proto-Oncogene Proteins c-kit
  • Serine Endopeptidases
  • Tryptases