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High-throughput functional assay in cystic fibrosis patient-derived organoids allows drug repurposing.
ERJ Open Res. 2023 Jan 30;9(1):00495-2022. doi: 10.1183/23120541.00495-2022. eCollection 2023 Jan.
ERJ Open Res. 2023.
PMID: 36726369
Free PMC article.
CRISPR-Based Adenine Editors Correct Nonsense Mutations in a Cystic Fibrosis Organoid Biobank.
Geurts MH, de Poel E, Amatngalim GD, Oka R, Meijers FM, Kruisselbrink E, van Mourik P, Berkers G, de Winter-de Groot KM, Michel S, Muilwijk D, Aalbers BL, Mullenders J, Boj SF, Suen SWF, Brunsveld JE, Janssens HM, Mall MA, Graeber SY, van Boxtel R, van der Ent CK, Beekman JM, Clevers H.
Geurts MH, et al. Among authors: brunsveld je.
Cell Stem Cell. 2020 Apr 2;26(4):503-510.e7. doi: 10.1016/j.stem.2020.01.019. Epub 2020 Feb 20.
Cell Stem Cell. 2020.
PMID: 32084388
Free article.
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Evaluating CRISPR-based prime editing for cancer modeling and CFTR repair in organoids.
Geurts MH, de Poel E, Pleguezuelos-Manzano C, Oka R, Carrillo L, Andersson-Rolf A, Boretto M, Brunsveld JE, van Boxtel R, Beekman JM, Clevers H.
Geurts MH, et al. Among authors: brunsveld je.
Life Sci Alliance. 2021 Aug 9;4(10):e202000940. doi: 10.26508/lsa.202000940. Print 2021 Oct.
Life Sci Alliance. 2021.
PMID: 34373320
Free PMC article.
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Forskolin-induced organoid swelling is associated with long-term cystic fibrosis disease progression.
Muilwijk D, de Poel E, van Mourik P, Suen SWF, Vonk AM, Brunsveld JE, Kruisselbrink E, Oppelaar H, Hagemeijer MC, Berkers G, de Winter-de Groot KM, Heida-Michel S, Jans SR, van Panhuis H, van der Eerden MM, van der Meer R, Roukema J, Dompeling E, Weersink EJM, Koppelman GH, Vries R, Zomer-van Ommen DD, Eijkemans MJC, van der Ent CK, Beekman JM.
Muilwijk D, et al. Among authors: brunsveld je.
Eur Respir J. 2022 Aug 18;60(2):2100508. doi: 10.1183/13993003.00508-2021. Print 2022 Aug.
Eur Respir J. 2022.
PMID: 35086832
Free PMC article.
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Forskolin induced swelling (FIS) assay in intestinal organoids to guide eligibility for compassionate use treatment in a CF patient with a rare genotype.
Aalbers BL, Brunsveld JE, van der Ent CK, van den Eijnden JC, Beekman JM, Heijerman HGM.
Aalbers BL, et al. Among authors: brunsveld je.
J Cyst Fibros. 2022 Mar;21(2):254-257. doi: 10.1016/j.jcf.2022.01.008. Epub 2022 Jan 31.
J Cyst Fibros. 2022.
PMID: 35110005
Free article.
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Measuring cystic fibrosis drug responses in organoids derived from 2D differentiated nasal epithelia.
Amatngalim GD, Rodenburg LW, Aalbers BL, Raeven HH, Aarts EM, Sarhane D, Spelier S, Lefferts JW, Silva IA, Nijenhuis W, Vrendenbarg S, Kruisselbrink E, Brunsveld JE, van Drunen CM, Michel S, de Winter-de Groot KM, Heijerman HG, Kapitein LC, Amaral MD, van der Ent CK, Beekman JM.
Amatngalim GD, et al. Among authors: brunsveld je.
Life Sci Alliance. 2022 Aug 3;5(12):e202101320. doi: 10.26508/lsa.202101320.
Life Sci Alliance. 2022.
PMID: 35922154
Free PMC article.
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FDA-approved drug screening in patient-derived organoids demonstrates potential of drug repurposing for rare cystic fibrosis genotypes.
de Poel E, Spelier S, Hagemeijer MC, van Mourik P, Suen SWF, Vonk AM, Brunsveld JE, Ithakisiou GN, Kruisselbrink E, Oppelaar H, Berkers G, de Winter de Groot KM, Heida-Michel S, Jans SR, van Panhuis H, Bakker M, van der Meer R, Roukema J, Dompeling E, Weersink EJM, Koppelman GH, Blaazer AR, Muijlwijk-Koezen JE, van der Ent CK, Beekman JM.
de Poel E, et al. Among authors: brunsveld je.
J Cyst Fibros. 2023 May;22(3):548-559. doi: 10.1016/j.jcf.2023.03.004. Epub 2023 May 3.
J Cyst Fibros. 2023.
PMID: 37147251
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Exploring intrinsic variability between cultured nasal and bronchial epithelia in cystic fibrosis.
Rodenburg LW, Metzemaekers M, van der Windt IS, Smits SMA, den Hertog-Oosterhoff LA, Kruisselbrink E, Brunsveld JE, Michel S, de Winter-de Groot KM, van der Ent CK, Stadhouders R, Beekman JM, Amatngalim GD.
Rodenburg LW, et al. Among authors: brunsveld je.
Sci Rep. 2023 Oct 30;13(1):18573. doi: 10.1038/s41598-023-45201-4.
Sci Rep. 2023.
PMID: 37903789
Free PMC article.
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