Outcomes of a radiation sparing approach in medulloblastoma by subgroup in young children: an institutional review

Childs Nerv Syst. 2023 Aug;39(8):2095-2104. doi: 10.1007/s00381-023-05918-z. Epub 2023 Apr 6.

Abstract

Objective: To describe disease outcomes including overall survival and relapse patterns by subgroup in young pediatric patients treated for medulloblastoma with a radiation-sparing approach.

Methods: Retrospective analysis of clinical outcomes includes treatment, relapse, and salvage therapy and late effects in children treated for medulloblastoma with a radiation-sparing approach at British Columbia Children's Hospital (BCCH) between 2000 and 2020.

Results: There were 30 patients (median age 2.8 years, 60% male) treated for medulloblastoma with a radiation-sparing approach at BCCH. Subgroups included Sonic Hedgehog (SHH) (n = 14), group 3 (n = 7), group 4 (n = 6), and indeterminate status (n = 3). Three- and 5-year event-free survival (EFS) were 49.0% (30.2-65.4%) and 42.0% (24.2-58.9%) and overall survival (OS) 66.0% (95% CI 46.0-80.1%) and 62.5% (95% CI 42.5 and 77.2%), respectively, with a median follow-up of 9.5 years. Relapse occurred in 12/25 patients following a complete response, of whom six (group 4: n = 4; group 3: n = 1; unknown: n = 1) were successfully salvaged with craniospinal axis (CSA) RT and remain alive at a median follow-up of 7 years. Disease/treatment-related morbidity included endocrinopathies (n = 8), hearing loss n = 16), and neurocognitive abnormalities (n = 9).

Conclusions: This radiation sparing treatment approach for young patients with medulloblastoma resulted in a durable cure in most patients with SHH subgroup medulloblastoma. In those patients with groups 3 and 4 medulloblastoma, relapse rates were high; however, most group 4 patients were salvaged with RT.

Keywords: Medulloblastoma; Neuro-oncology; Oncology; Pediatric; Radiation; Survivorship.

MeSH terms

  • Cerebellar Neoplasms* / drug therapy
  • Child
  • Child, Preschool
  • Female
  • Hedgehog Proteins
  • Humans
  • Male
  • Medulloblastoma* / drug therapy
  • Recurrence
  • Retrospective Studies

Substances

  • Hedgehog Proteins