MG132 Induces Progerin Clearance and Improves Disease Phenotypes in HGPS-like Patients' Cells

Cells. 2022 Feb 10;11(4):610. doi: 10.3390/cells11040610.

Abstract

Progeroid syndromes (PS), including Hutchinson-Gilford Progeria Syndrome (HGPS), are premature and accelerated aging diseases, characterized by clinical features mimicking physiological aging. Most classical HGPS patients carry a de novo point mutation within exon 11 of the LMNA gene encoding A-type lamins. This mutation activates a cryptic splice site, leading to the production of a truncated prelamin A, called prelamin A ∆50 or progerin, that accumulates in HGPS cell nuclei and is a hallmark of the disease. Some patients with PS carry other LMNA mutations and are named "HGPS-like" patients. They produce progerin and/or other truncated prelamin A isoforms (∆35 and ∆90). We previously found that MG132, a proteasome inhibitor, induced progerin clearance in classical HGPS through autophagy activation and splicing regulation. Here, we show that MG132 induces aberrant prelamin A clearance and improves cellular phenotypes in HGPS-like patients' cells other than those previously described in classical HGPS. These results provide preclinical proof of principle for the use of a promising class of molecules toward a potential therapy for children with HGPS-like or classical HGPS.

Keywords: MAD-B; MG132; autophagy; inflammation; prelamin A Δ35; prelamin A Δ90; progeria-like; progerin.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Cell Nucleus
  • Humans
  • Leupeptins / pharmacology
  • Leupeptins / therapeutic use
  • Phenotype
  • Progeria* / drug therapy
  • Progeria* / genetics

Substances

  • Leupeptins
  • benzyloxycarbonylleucyl-leucyl-leucine aldehyde