Macular edema in Cogan-Reese syndrome

Hugo Bouvarel; Pascale Hamard; Emilie Agard; Jérémy Billant; Hussam El Chehab; Corinne Dot

doi:10.1016/j.ajoc.2022.101318

Macular edema in Cogan-Reese syndrome

Am J Ophthalmol Case Rep. 2022 Jan 26:25:101318. doi: 10.1016/j.ajoc.2022.101318. eCollection 2022 Mar.

Authors

Hugo Bouvarel¹, Pascale Hamard², Emilie Agard¹, Jérémy Billant¹, Hussam El Chehab¹, Corinne Dot¹

Affiliations

¹ Hôpital d'Instruction des Armées Desgenettes, 108 Boulevard Pinel, 69003, Lyon, France.
² Centre Hospitalier National d'Ophtalmologie des Quinze-Vingts, 28 Rue de Charenton, 75012, Paris, France.

Abstract

Purpose: Iridocorneo-endothelial (ICE) syndrome is known as a rare spectrum causing glaucoma, corneal and iris damages. Retinal complications are uncommon.

Observations: We report the case of a middle-aged woman suffering from a Cogan-Reese Syndrome (CRS) with refractory ocular hypertension (OHT) who presented a cystoid macular edema (CME) during follow up.

Conclusions and importance: We suspect the CME to be inflammatory linked to the pathophysiological hypotheses of the CRS. The CME was successfully treated with topical nonsteroidal anti-inflammatory drugs (NSAID). No consensus is available on its duration. A recurrence happened when treatment was stopped, its reintroduction was successful.

Keywords: Case report; Glaucoma; Iridocorneal endothelial syndrome; Macular edema.

Publication types

Case Reports