Porphyric Neuropathy: Pathophysiology, Diagnosis, and Updated Management

Curr Neurol Neurosci Rep. 2020 Oct 7;20(12):56. doi: 10.1007/s11910-020-01078-8.

Abstract

Purpose of review: To review the peripheral neurological complications of the acute hepatic porphyrias, as well as the latest advances in their pathophysiology and management.

Recent findings: The diagnosis of porphyric neuropathy remains challenging as varying neuropathic patterns are encountered depending on disease stage, including a non-length-dependent distribution pattern. The major pathophysiologic mechanism is δ-aminolevulinic acid (ALA)-induced neurotoxicity. The less restrictive blood-nerve barrier in the autonomic ganglia and myenteric plexus may explain the frequency of dysautonomic manifestations. Recently, a prophylactic small interfering RNA (siRNA)-based therapy that reduces hepatic ALA Synthase-1 mRNA was approved for patients with recurrent neuro-visceral attacks. Neurologists should appreciate the varying patterns of porphyric neuropathy. As with most toxin-induced axonopathies, long-term outcomes depend on early diagnosis and treatment. While the short-term clinical and biochemical benefits of siRNA-based therapy are known, its long-term effects on motor recovery, chronic pain, and dysautonomic manifestations are yet to be determined.

Keywords: ALA; Dysautonomia; Hemin; Neuropathy; Porphyria; Small interfering RNA.

Publication types

  • Review

MeSH terms

  • Humans
  • Peripheral Nervous System Diseases* / diagnosis
  • Peripheral Nervous System Diseases* / therapy
  • Polyneuropathies*
  • Porphobilinogen Synthase
  • Porphyrias, Hepatic*

Substances

  • Porphobilinogen Synthase