Congenital oral synechia and ankyloblepharon filiforme adnatum: Case report and literature review

Int J Pediatr Otorhinolaryngol. 2016 Nov:90:196-199. doi: 10.1016/j.ijporl.2016.09.023. Epub 2016 Sep 20.

Abstract

Introduction: Congenital intraoral synechias are adhesions of intraoral structures involving soft tissue. These conditions and another anomaly called ankyloblepharon filiforme adnatum, which is partial fusion of the eyelid margins by bands of tissue, are rarely reported in the literature. The association of both anomalies of the craniomaxillofacial region is an even more unusual finding.

Purpose: This article adds more information to the literature by reporting a case of a neonate with a rare association of bilateral synechia between the jaws, fusion of buccal mucosa to the ridges and between the tongue and palate, and ankyloblepharon filiforme adnatum in both eyes, without any other facial or systemic malformation.

Methods: A literature review of similar cases published in PUBMED/MEDLINE was conducted followed by a discussion and comparison to the new case.

Conclusion: The rare association of these congenital defects, without the presence of syndromic symptoms, could be diagnosed and treated easily with good prognostic evolution.

Keywords: Ankyloblepharon filiforme adnatum; Congenital defects; Ectopic tissue; Jaw abnormality.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Cleft Lip / complications
  • Cleft Lip / diagnosis*
  • Cleft Lip / surgery
  • Cleft Palate / complications
  • Cleft Palate / diagnosis*
  • Cleft Palate / surgery
  • Eye Abnormalities / complications
  • Eye Abnormalities / diagnosis*
  • Eye Abnormalities / surgery
  • Female
  • Humans
  • Infant, Newborn
  • Mouth Abnormalities / complications
  • Mouth Abnormalities / diagnosis*
  • Mouth Abnormalities / surgery
  • Mouth Mucosa
  • Tissue Adhesions / diagnosis*
  • Tissue Adhesions / surgery
  • Tongue

Supplementary concepts

  • Ankyloblepharon filiforme adnatum