Increased frequency of rhabdomyolysis in familial dysautonomia

Muscle Nerve. 2015 Nov;52(5):887-90. doi: 10.1002/mus.24781. Epub 2015 Aug 13.

Abstract

Introduction: Familial dysautonomia (FD; OMIM # 223900) is an autosomal recessive disease with features of impaired pain and temperature perception and lack of functional muscle spindles. After 3 FD patients presented with rhabdomyolysis in a short time span, we aimed to determine the frequency of rhabdomyolysis is this population.

Methods: This study was a retrospective chart review of 665 FD patients.

Results: Eight patients had at least 1 episode of rhabdomyolysis. Two patients had 2 episodes. The average incidence of rhabdomyolysis in FD was 7.5 per 10,000 person-years. By comparison, the average incidence with statins has been reported to be 0.44 per 10,000 person-years. Mean maximum creatine kinase (CK) level was 32,714 ± 64,749 U/L. Three patients had hip magnetic resonance imaging showing gluteal hyperintensities.

Conclusions: Patients with FD have an increased incidence of rhabdomyolysis. We hypothesize that this may result from a combination of absent functional muscle spindles and muscle mitochondrial abnormalities.

Keywords: autonomic disorders; creatine kinase; hereditary sensory autonomic neuropathy; mitochondria; skeletal muscle.

Publication types

  • Research Support, N.I.H., Extramural

MeSH terms

  • Adolescent
  • Child
  • Dysautonomia, Familial / complications*
  • Dysautonomia, Familial / diagnosis*
  • Female
  • Follow-Up Studies
  • Humans
  • Male
  • Retrospective Studies
  • Rhabdomyolysis / complications*
  • Rhabdomyolysis / diagnosis*
  • Young Adult