[In vitro expression study of novel mutations in phenylalanine hydroxylase gene]

Zhonghua Yi Xue Yi Chuan Xue Za Zhi. 2013 Dec;30(6):673-7. doi: 10.3760/cma.j.issn.1003-9406.2013.06.009.
[Article in Chinese]

Abstract

Objective: To study the in vitro expression of 6 novel missense mutations (R270G, P275A, F121L, A156P, E183G, I324N) and a previously described R408Q mutation of phenylalanine hydroxylase (PAH) gene and explore the genotype-phenotype correlation through comparison of protein levels and residual enzyme activities.

Methods: Seven expression vectors containing PAH cDNA were constructed with a site-directed mutagenesis kit. The plasmids were extracted and sequenced to confirm the target mutations. pcDNA3.0 containing PAH cDNA was transfected into COS-7 cells and total proteins were extracted 48 h after transfection. The quantities of proteins and residual enzyme activities of the 7 mutants were assessed with the wild-type PAH gene as reference.

Results: Relative quantities of PAH proteins for R270G, P275A, F121L, A156P, E183G, I324N and R408Q were 10.5%, 56.6%, 54.3%, 8.7%, 8.5%, 67.3% and 85.4%, respectively. The residual enzyme activities were 7.7%, 27.6%, 19.0%, 10.4%, 9.1%, 50.6% and 40.2%, respectively.

Conclusion: PAH residual enzyme activities of 7 PAH mutants were all significantly reduced.

MeSH terms

  • Amino Acid Sequence
  • Animals
  • COS Cells
  • Chlorocebus aethiops
  • Genetic Association Studies / methods
  • Humans
  • Molecular Sequence Data
  • Mutation, Missense*
  • Phenylalanine Hydroxylase / genetics*
  • Sequence Alignment

Substances

  • Phenylalanine Hydroxylase