Atypical Cogan's syndrome presenting as bilateral endogenous endophthalmitis

Clin Exp Optom. 2014 Jan;97(1):87-9. doi: 10.1111/j.1444-0938.2012.00787.x. Epub 2012 Aug 22.

Abstract

We report a case of atypical Cogan's syndrome presenting as bilateral endogenous endophthalmitis in a woman with ovarian cancer. A 62-year-old woman with ovarian cancer developed bilateral interstitial keratitis and panuveitis accompanied by bilateral sensorineural hearing loss and chondritis. Auricular cartilage biopsy ruled out relapsing polychondritis and the diagnosis of atypical Cogan's syndrome was set clinically.

Keywords: atypical Cogan's syndrome; chondritis; endophthalmitis; ovarian cancer; relapsing polychondritis.

Publication types

  • Case Reports

MeSH terms

  • Cogan Syndrome / complications
  • Cogan Syndrome / diagnosis*
  • Cogan Syndrome / pathology
  • Diagnosis, Differential
  • Endophthalmitis / complications
  • Endophthalmitis / diagnosis*
  • Endophthalmitis / pathology
  • Female
  • Hearing Loss, Sensorineural / complications
  • Humans
  • Keratitis / complications
  • Keratitis / diagnosis*
  • Keratitis / pathology
  • Middle Aged
  • Ovarian Neoplasms / complications*
  • Polychondritis, Relapsing / complications
  • Polychondritis, Relapsing / diagnosis*
  • Polychondritis, Relapsing / pathology