Adenovirus-mediated stem cell leukemia gene transfer induces rescue of interstitial cells of Cajal in ICC-loss mice

Int J Colorectal Dis. 2010 May;25(5):557-66. doi: 10.1007/s00384-010-0883-z. Epub 2010 Feb 18.

Abstract

Objective: Interaction of c-Kit and its ligand stem cell factor (SCF) is necessary for appropriate development and survival of interstitial cells of Cajal (ICC) in the intestine. Blockade of c-Kit will cause ICC loss in vivo. Stem cell leukemia (SCL) gene acts as a positive regulator of upstream transcription of c-Kit expression. This study aimed to explore whether the restoration of c-Kit expression promoted by SCL gene transfer could rescue ICC in vivo.

Materials and methods: A modified ICC-loss mouse model was created by continual administration of anti-c-Kit antibody (ACK2) to obtain a steady status of ICC loss, and a recombinant adenovirus vector containing SCL gene (Ad-SCL) was designed to rescue ICC in these mice. Western blot analysis and immunofluorescence labeling assays were performed to analyze the SCL and c-Kit expression in vitro and in vivo. The distribution and configuration of ICC were observed with immunohistochemistry and electromicroscope.

Results: Western blot analysis and immunofluorescence labeling assays showed that SCL gene was successfully delivered to cultured HeLa and ICC cells in vitro. Moreover, significantly increased c-Kit expression could be detected in the colon of Ad-SCL-infected ICC-loss mice. Furthermore, rescue of the ICC network and ICC with typical ultrastructural features could be detected in Ad-SCL-infected ICC-loss mice at day 37.

Conclusions: Ad-SCL was able to enhance c-Kit expression, reactivate the c-Kit/SCF pathway, and rescue ICC in ICC-loss mice. Since loss and defects of ICC are associated with many human gut motility disorders, Ad-SCL may be of potential use in gene therapy of these patients.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adenoviridae / genetics*
  • Animals
  • Basic Helix-Loop-Helix Transcription Factors / metabolism*
  • Cell Shape
  • Colon / pathology
  • Colon / ultrastructure
  • Disease Models, Animal
  • Gene Transfer Techniques*
  • HeLa Cells
  • Humans
  • Interstitial Cells of Cajal / pathology*
  • Interstitial Cells of Cajal / ultrastructure
  • Leukemia / pathology*
  • Mice
  • Mice, Inbred BALB C
  • Proto-Oncogene Proteins c-kit / metabolism
  • Recombination, Genetic
  • Reproducibility of Results
  • Staining and Labeling
  • Stem Cells / metabolism*

Substances

  • Basic Helix-Loop-Helix Transcription Factors
  • Proto-Oncogene Proteins c-kit