Clinical risk factors for mortality in patients with neurofibromatosis 1: a cohort study of 378 patients

Arch Dermatol. 2003 Feb;139(2):187-91. doi: 10.1001/archderm.139.2.187.

Abstract

Objective: To identify the main clinical features associated with mortality in patients with neurofibromatosis 1.

Design: Cohort study.

Setting: Referral center for neurofibromatosis.

Patients: Three hundred seventy-eight patients with neurofibromatosis 1 who had more than 1 year of follow-up in the center.

Main outcome measures: Mortality. Clinical features, especially dermatological, were evaluated as potential factors associated with mortality.

Results: Factors associated independently with mortality were the presence of subcutaneous neurofibromas (odds ratio, 10.8; 95% confidence interval, 2.1-56.7; P<.001), the absence of cutaneous neurofibromas (odds ratio, 5.3; 95% confidence interval, 1.2-25.0; P =.03), and facial asymmetry (odds ratio, 11.4; 95% confidence interval, 2.6-50.2; P<.01).

Conclusions: Some features that can be found by a routine clinical examination are associated with mortality in patients with neurofibromatosis 1. Clinical follow-up should be focused on patients with subcutaneous neurofibromas and/or the absence of cutaneous neurofibromas and/or facial asymmetry.

Publication types

  • Research Support, Non-U.S. Gov't

MeSH terms

  • Adolescent
  • Adult
  • Age Distribution
  • Aged
  • Biopsy, Needle
  • Cause of Death*
  • Child
  • Cohort Studies
  • Confidence Intervals
  • Female
  • France / epidemiology
  • Humans
  • Incidence
  • Male
  • Middle Aged
  • Multivariate Analysis
  • Neoplasm Staging
  • Neurofibromatosis 1 / mortality*
  • Neurofibromatosis 1 / pathology*
  • Neurofibromatosis 1 / therapy
  • Odds Ratio
  • Probability
  • Registries
  • Risk Factors
  • Sex Distribution
  • Skin Neoplasms / mortality*
  • Skin Neoplasms / pathology*
  • Skin Neoplasms / therapy
  • Survival Analysis